May 2007
Volume 48, Issue 13
Free
ARVO Annual Meeting Abstract  |   May 2007
Mutation Screen of Complement Regulator Genes in Patients With Age-Related Macular Degeneration
Author Affiliations & Notes
  • G. J. Pauer
    Cole Eye Institute i-31, Cleveland Clinic Foundation, Cleveland, Ohio
  • U. Narendra
    Cole Eye Institute i-31, Cleveland Clinic Foundation, Cleveland, Ohio
  • E. Simpson
    Cole Eye Institute i-31, Cleveland Clinic Foundation, Cleveland, Ohio
  • H. Lewis
    Cole Eye Institute i-31, Cleveland Clinic Foundation, Cleveland, Ohio
    Case Western Reserve University, Cleveland, Ohio
  • S. A. Hagstrom
    Cole Eye Institute i-31, Cleveland Clinic Foundation, Cleveland, Ohio
    Case Western Reserve University, Cleveland, Ohio
  • Footnotes
    Commercial Relationships G.J. Pauer, None; U. Narendra, None; E. Simpson, None; H. Lewis, None; S.A. Hagstrom, None.
  • Footnotes
    Support NIH Grant EY15638, Karl Kirschgessner Foundation, Research to Prevent Blindness, Foundation Fighting Blindness, State of Ohio - BRTT Grant
Investigative Ophthalmology & Visual Science May 2007, Vol.48, 4622. doi:
  • Views
  • Share
  • Tools
    • Alerts
      ×
      This feature is available to authenticated users only.
      Sign In or Create an Account ×
    • Get Citation

      G. J. Pauer, U. Narendra, E. Simpson, H. Lewis, S. A. Hagstrom; Mutation Screen of Complement Regulator Genes in Patients With Age-Related Macular Degeneration. Invest. Ophthalmol. Vis. Sci. 2007;48(13):4622.

      Download citation file:


      © ARVO (1962-2015); The Authors (2016-present)

      ×
  • Supplements
Abstract

Purpose:: Age-related macular degeneration (AMD) is the most common form of irreversible blindness in developed countries. Sequence variants in the complement factor H gene (CFH), which encodes a major regulator of the complement pathway, are associated with the risk for developing AMD. We evaluated whether variations in genes encoding other regulatory proteins of the same complement pathway are associated with AMD. We screened membrane cofactor protein (MCP) and decay-accelerating factor (DAF) - inhibitors of complement activation, and complement factor H related protein 5 (CFHR5) - a protein homologous to CFH and proposed to function in complement regulation.

Methods:: To date, a partial mutation screen of MCP (12 out of 13 coding exons), DAF (4 out of 10 coding exons), and CFHR5 (8 out of 10 coding exons) has been performed in 665 unrelated patients with AMD using direct genomic sequencing.

Results:: No sequence changes have been identified in MCP, DAF, or CFHR5.

Conclusions:: Although we have not completed these screens, we have found no sequence changes in three genes involved in regulating the complement cascade, MCP, DAF and CFHR5. Results to date indicate that defects in these genes are unlikely to be associated with AMD. However, we are completing our evaluation of the remaining exons in these patients.

Keywords: age-related macular degeneration • candidate gene analysis • mutations 
×
×

This PDF is available to Subscribers Only

Sign in or purchase a subscription to access this content. ×

You must be signed into an individual account to use this feature.

×