Investigative Ophthalmology & Visual Science Cover Image for Volume 61, Issue 7
June 2020
Volume 61, Issue 7
Free
ARVO Annual Meeting Abstract  |   June 2020
Clinical and In Vivo Confocal Microscopy Features of Patients with Systemic Small Fiber Polyneuropathy Presenting with Neuropathic Corneal Pain
Author Affiliations & Notes
  • Stephanie Cox
    Center for Translational Ocular Immunology, Department of Ophthalmology, Tufts Medical Center, Tufts University School of Medicine, Boston, Massachusetts, United States
  • Nairi K Strauch
    School of Medicine, Tufts University, Boston, Massachusetts, United States
  • Marianna C Athanassiou
    School of Medicine, Tufts University, Boston, Massachusetts, United States
  • Betul Bayraktutar
    Center for Translational Ocular Immunology, Department of Ophthalmology, Tufts Medical Center, Tufts University School of Medicine, Boston, Massachusetts, United States
  • Pedram Hamrah
    Center for Translational Ocular Immunology, Department of Ophthalmology, Tufts Medical Center, Tufts University School of Medicine, Boston, Massachusetts, United States
    Cornea Service, New England Eye Center; Department of Ophthalmology, Tufts Medical Center, Tufts University School of Medicine, Boston, Massachusetts, United States
  • Footnotes
    Commercial Relationships   Stephanie Cox, None; Nairi Strauch, None; Marianna Athanassiou, None; Betul Bayraktutar, None; Pedram Hamrah, None
  • Footnotes
    Support  NIH-1R61NS113341-01, Research to Prevent Blindness Challenge Grant, Massachusetts Lions Eye Research Fund, Inc. Tufts Institutional Support, Imaging Fellowship from Heidelberg Engineering
Investigative Ophthalmology & Visual Science June 2020, Vol.61, 4087. doi:
  • Views
  • Share
  • Tools
    • Alerts
      ×
      This feature is available to authenticated users only.
      Sign In or Create an Account ×
    • Get Citation

      Stephanie Cox, Nairi K Strauch, Marianna C Athanassiou, Betul Bayraktutar, Pedram Hamrah; Clinical and In Vivo Confocal Microscopy Features of Patients with Systemic Small Fiber Polyneuropathy Presenting with Neuropathic Corneal Pain. Invest. Ophthalmol. Vis. Sci. 2020;61(7):4087.

      Download citation file:


      © ARVO (1962-2015); The Authors (2016-present)

      ×
  • Supplements
Abstract

Purpose : A previous study showed that patients with small fiber neuropathy (SFN), but no ocular symptoms, often have reduced corneal nerve density. However, investigations of SFN patients with ocular discomfort have not been reported. This case series aims to highlight the clinical and in vivo confocal microscopy (IVCM) presentation of patients with SFN presenting with ocular discomfort.

Methods : This case series presents three patients who presented with neuropathic corneal pain (NCP) and were determined to have systemic SFN as proven by skin biopsy with decreased neurites. The patients were diagnosed with NCP based on their clinical presentation and IVCM findings. Demographics, clinical characteristics for signs and symptoms, as well as impact on quality of life were recorded. The nerve density for each subject was calculated by averaging the density of three selected images using NeuronJ.

Results : The average age of the two female and one male patient was 52.3±9.9 years. The average Ocular Surface Disease Index Score was 74.1±19.5. The average OPAS 24 hour eye pain intensity score and 2-week eye pain intensity score was 8.1±1.7 and 7.8±1.9 (scale 0-10), respectively. The average OPAS non-eye pain score was 4.7±4.1. The average OPAS quality of life score was 6.7±0.1, and the average aggravating factors score and associated factors score was 6.8±1.9 and 5.6±0.4, respectively. The mean corneal staining and Schirmer’s score were 1.3±1.5 and 2.3±2.5 mm, respectively. The percent presumed centralized pain averaged at 72.5±19.6%. The average mean nerve density via IVCM was 12,343.38±7,185.11 mm/mm2. The patient with the lowest nerve density had the least centralized pain, but the patient with the most centralized pain displayed the highest nerve density. All patients were referred for skin biopsy that demonstrated decreased neurites.

Conclusions : SFN patients can initially present with NCP, which may manifest with variable levels or corneal nerve density, depending on contribution of pain due to centralized sensitization.

This is a 2020 ARVO Annual Meeting abstract.

×
×

This PDF is available to Subscribers Only

Sign in or purchase a subscription to access this content. ×

You must be signed into an individual account to use this feature.

×